000K  utf8
1100  2021$c2021-02-27
1500  eng
2050  urn:nbn:de:hbz:465-20240828-114459-7
2051  10.1186/s13023-021-01750-3
3000  Bonella, Francesco
3010  Boerner, Eda
3010  Campo, Ilaria
3010  Costabel, Ulrich
3010  Ohshimo, Shinichiro
3010  Taube, Christian
3010  Theegarten, Dirk
3010  Zorzetto, Michele
4000  Potential clinical utility of MUC5B und TOLLIP single nucleotide polymorphisms (SNPs) in the management of patients with IPF  [Bonella, Francesco]
4209  Background: Genetic variants of TOLLIP and MUC5B, both on chromosome 11, have been reported to be associated with the development and/or prognosis of idiopathic pulmonary fibrosis (IPF). This retrospective study was conducted to investigate the association of MUC5B and TOLLIP SNPs with disease outcome in IPF. 62 IPF patients and 50 healthy controls (HC) from our Institution were genotyped for SNPs within MUC5B (rs35705950) and TOLLIP (rs3750920 and rs5743890). Correlation of SNPs genotypes with survival, acute exacerbation (AE) or disease progression (defined as a decline of ≥ 5% in FVC and or ≥ 10% in DLco in one year) was investigated. Results: The MUC5B rs35705950 minor allele (T) was more frequent in IPF subjects than in HC (35% vs 9% p  < 0.001). TOLLIP SNPs alleles and genotype distribution did not differ between IPF and HC and did not vary according to gender, age, BMI and lung functional impairment at baseline. The minor allele (C) in TOLLIP rs5743890 was associated with worse survival and with disease progression in all performed analyses. The MUC5B rs35705950 or the TOLLIP rs3750920 minor allele, were not associated with disease progression or AE. Conclusion: We confirm that the minor allele of MUC5B rs35705950 is associated with IPF. The minor allele of TOLLIP rs5743890 appears to be a predictor of worse survival and more rapid disease progression, therefore being of potential utility to stratify IPF patients at baseline.
4950  https://doi.org/10.1186/s13023-021-01750-3$xR$3Volltext$534
4950  https://nbn-resolving.org/urn:nbn:de:hbz:465-20240828-114459-7$xR$3Volltext$534
4961  https://duepublico2.uni-due.de/receive/duepublico_mods_00077608
5051  610
5550  Disease progression
5550  IPF
5550  MUC5B
5550  TOLLIP